A homozygous mutation in PEX16 identified by whole-exome sequencing ending a diagnostic odyssey

نویسندگان

  • Carlos A. Bacino
  • Yu-Hsin Chao
  • Elaine Seto
  • Tim Lotze
  • Fan Xia
  • Richard O. Jones
  • Ann Moser
  • Michael F. Wangler
چکیده

We present a patient with a unique neurological phenotype with a progressive neurodegenerative phenotype. An 18-year diagnostic odyssey for the patient ended when exome sequencing identified a homozygous PEX16 mutation suggesting an atypical peroxisomal biogenesis disorder (PBD). Interestingly, the patient's peroxisomal biochemical abnormalities were subtle, such that plasma very-long-chain fatty acids initially failed to provide a diagnosis. This case suggests next-generation sequencing may be diagnostic in some atypical peroxisomal biogenesis disorders.

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عنوان ژورنال:

دوره 5  شماره 

صفحات  -

تاریخ انتشار 2015